Estimating the cis -heritability of gene expression using single cell expression profiles controls false positive rate of eGene detection.

Xu, Ziqi, Arya Massarat, Laurie Rumker, Melissa Gymrek, Soumya Raychaudhuri, Wei Zhou, and Tiffany Amariuta. 2025. “Estimating the Cis -Heritability of Gene Expression Using Single Cell Expression Profiles Controls False Positive Rate of EGene Detection.”. BioRxiv : The Preprint Server for Biology.

Abstract

For gene expression traits, cis -genetic heritability can quantify the strength of genetic regulation in particular cell types, elucidating the cell-type-specificity of disease variants and genes. To estimate gene expression heritability, standard models require a single gene expression value per individual, forcing data from single cell RNA-sequencing (scRNA-seq) experiments to be "pseudobulked". Here, we show that applying standard heritability models to pseudobulk data overestimates gene expression heritability and produces inflated false positive rates for detecting cis -heritable genes. Therefore, we introduce a new method called scGeneHE ( s ingle c ell Gene expression H eritability E stimation), a Poisson mixed-effects model that quantifies the cis -genetic component of gene expression using individual cellular profiles. In simulations, scGeneHE has a consistently well-calibrated false positive rate for eGene detection and unbiasedly estimates cis -heritability at many parameter settings. We applied scGeneHE to scRNA-seq data from 969 individuals, 11 immune cell types, and 822,552 cells from the OneK1K cohort to infer cell-type-specificity of genetic regulation at risk genes for immune-mediated diseases and trace the fluctuation of cis -heritability across cellular populations of varying resolution. In summary, we developed a new statistical method that resolves the analytical challenge of estimating gene expression cis -heritability from native scRNA-seq data.

Last updated on 03/10/2025
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